Use of a closed set questionnaire to measure primary and secondary effects of neurofibromatosis type 2

作者：Neary W J^*; Hillier V F; Flute T; Stephens D; Ramsden R T; Evans D G R

来源：Journal of Laryngology and Otology, 2010, 124(7): 720-728.

DOI：10.1017/S0022215110000460

• Neurofibromatosis Type 2
• Communication Difficulties
• Psychosocial Effects

Objectives: To identify the greatest difficulties reported by people affected by neurofibromatosis type 2, and to determine the relationship between the primary and secondary effects of the disease.
Design: Postal questionnaire study.
Setting: Questionnaire sent to subjects' home addresses.
Participants: Eighty-seven adult patients under the care of the Manchester multidisciplinary neurofibromatosis type 2 team were invited to take part.
Main outcome measure: The response rate was 62 out of 87 (71 per cent).
Results: Respondents' answers emphasised that their greatest problem was deafness, which resulted in communication difficulties with social contacts, close partners, family and friends. Correlation coefficients indicated a relationship between general mood changes and hearing difficulties, social communication problems, balance difficulties and mobility problems. Self-confidence was significantly related only to social communication problems.
Conclusions: The use of a closed set neurofibromatosis type 2 questionnaire identified hearing problems and subsequent communication difficulties as the main problems faced by people with this condition.

• 出版日期2010-7